COPB1

Chr 11AR

coat protein complex I subunit beta 1

Also known as: BARMACS, COPB

The COPB1 protein is a subunit of the coatomer complex that mediates vesicular transport between the endoplasmic reticulum and Golgi apparatus, playing essential roles in protein trafficking, lipid homeostasis, and cellular compartmentalization. Mutations cause Baralle-Macken syndrome, an autosomal recessive disorder. This gene is highly constrained against loss-of-function mutations (pLI 0.999, LOEUF 0.213), indicating that haploinsufficiency is likely not tolerated in the general population.

Summary from RefSeq, OMIM, UniProt
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Primary Disease Associations & Inheritance

Baralle-Macken syndromeMIM #619255
AR
0
Active trials
9
Pubs (1 yr)
0
P/LP submissions
P/LP missense
0.21
LOEUF· LoF intol.
Mechanism
Clinical SummaryCOPB1
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.21LOEUF
pLI 1.000
Z-score 5.85
OE 0.10 (0.050.21)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
2.38Z-score
OE missense 0.70 (0.640.77)
354 obs / 504.6 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.10 (0.050.21)
00.351.4
Missense OE0.70 (0.640.77)
00.61.4
Synonymous OE0.93
01.21.6
LoF obs/exp: 5 / 49.4Missense obs/exp: 354 / 504.6Syn Z: 0.76

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

COPB1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗