CHTF8

Chr 16

chromosome transmission fidelity factor 8

Also known as: CTF8, DERPC

The protein forms part of the CTF18-RFC complex that loads PCNA onto DNA during replication and repair, and is essential for sister chromatid cohesion and faithful chromosome transmission. Loss-of-function mutations cause an autosomal recessive intellectual disability syndrome with microcephaly and growth retardation. The pathogenic mechanism involves defective DNA replication and chromosome cohesion leading to genomic instability during development.

Summary from RefSeq, UniProt, Mechanism
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0
Active trials
0
Pubs (1 yr)
0
P/LP submissions
P/LP missense
0.99
LOEUF
LOF
Mechanism· predicted
Clinical SummaryCHTF8
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.21) despite low pLI — interpret in context.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.99LOEUF
pLI 0.373
Z-score 1.60
OE 0.21 (0.070.99)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.29Z-score
OE missense 0.90 (0.741.11)
65 obs / 72.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.21 (0.070.99)
00.351.4
Missense OE0.90 (0.741.11)
00.61.4
Synonymous OE0.92
01.21.6
LoF obs/exp: 1 / 4.8Missense obs/exp: 65 / 72.0Syn Z: 0.33
DN
0.3395th %ile
GOF
0.11100th %ile
LOF
0.68top 10%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

CHTF8 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found