CHCHD10

Chr 22AD

coiled-coil-helix-coiled-coil-helix domain containing 10

Also known as: C22orf16, FTDALS2, IMMD, MIX17A, N27C7-4, SMAJ

This gene encodes a mitochondrial protein that is enriched at cristae junctions in the intermembrane space. It may play a role in cristae morphology maintenance or oxidative phosphorylation. Mutations in this gene cause frontotemporal dementia and/or amyotrophic lateral sclerosis-2. Alternative splicing of this gene results in multiple transcript variants. Related pseudogenes have been identified on chromosomes 7 and 19. [provided by RefSeq, Aug 2014]

GeneReviewsOMIMResearchGenerating clinical summary…

Primary Disease Associations & Inheritance

?Myopathy, isolated mitochondrial, autosomal dominantMIM #616209
AD
Frontotemporal dementia and/or amyotrophic lateral sclerosis 2MIM #615911
AD
Spinal muscular atrophy, Jokela typeMIM #615048
AD

Clinical highlights

Gene-disease validity (ClinGen)
mitochondrial disease · ADDefinitivesufficient evidence for diagnostic panels2 gene-disease associations curated in total
5
Active trials
38
Pubs (1 yr)
P/LP submissions
P/LP missense
1.91
LOEUF
Multiple*
Mechanism· predicted
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GeneReview available — CHCHD10
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Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint?
1.91LOEUF
pLI 0.000
Z-score -0.75
OE 1.35 (0.731.91)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint?
0.82Z-score
OE missense 0.71 (0.560.91)
47 obs / 65.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios?
LoF OE?1.35 (0.731.91)
00.351.4
Missense OE?0.71 (0.560.91)
00.61.4
Synonymous OE?1.09
01.21.6
LoF obs/exp: 7 / 5.2Missense obs/exp: 47 / 65.8Syn Z: -0.41

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

CHCHD10 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.