CFAP96

Chr 4

cilia and flagella associated protein 96

The protein localizes to non-motile cilia, centrosomes, and cytoplasmic microtubules where it likely functions in ciliary structure or signaling. Mutations cause autosomal recessive retinal dystrophy and Bardet-Biedl syndrome, ciliopathies that can present with vision loss, obesity, kidney dysfunction, and developmental delays. The gene shows minimal constraint against loss-of-function variants, consistent with recessive inheritance where one functional copy is insufficient.

ResearchSummary from RefSeq
LOEUF 1.02
Clinical SummaryCFAP96
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
Some data sources returned errors (1)

ncbi: Error: NCBI fetch failed: 429 https://eutils.ncbi.nlm.nih.gov/entrez/eutils/esearch.fcgi

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.02LOEUF
pLI 0.001
Z-score 1.53
OE 0.54 (0.311.02)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
1.23Z-score
OE missense 0.71 (0.600.84)
101 obs / 142.5 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.54 (0.311.02)
00.351.4
Missense OE0.71 (0.600.84)
00.61.4
Synonymous OE1.00
01.21.6
LoF obs/exp: 7 / 12.9Missense obs/exp: 101 / 142.5Syn Z: 0.02

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

CFAP96 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →