CENPV

Chr 17

centromere protein V

Also known as: 3110013H01Rik, CENP-V, PRR6, p30

The protein is required for centromere formation and organization, chromosome alignment, and cytokinesis, and is essential for proper distribution of pericentromeric heterochromatin during cell division. Mutations in this gene cause autosomal recessive primary microcephaly with seizures and developmental delay. The gene shows moderate tolerance to loss-of-function variants, which is consistent with the recessive inheritance pattern observed in affected individuals.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 0.74
Clinical SummaryCENPV
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.23) despite low pLI — interpret in context.
📋
ClinVar Variants
25 unique Pathogenic / Likely Pathogenic· 54 VUS of 87 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.74LOEUF
pLI 0.332
Z-score 2.08
OE 0.23 (0.100.74)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
1.44Z-score
OE missense 0.63 (0.520.76)
75 obs / 119.3 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.23 (0.100.74)
00.351.4
Missense OE0.63 (0.520.76)
00.61.4
Synonymous OE0.97
01.21.6
LoF obs/exp: 2 / 8.6Missense obs/exp: 75 / 119.3Syn Z: 0.16

ClinVar Variant Classifications

87 submitted variants in ClinVar

Classification Summary

Pathogenic25
VUS54
Likely Benign2
Benign1
25
Pathogenic
54
VUS
2
Likely Benign
1
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
25
0
25
Likely Pathogenic
0
0
0
0
0
VUS
0
36
18
0
54
Likely Benign
0
1
1
0
2
Benign
0
1
0
0
1
Total03844082

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

CENPV · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC