CDC123

Chr 10

cell division cycle 123

Also known as: C10orf7, D123

The CDC123 protein functions as an ATP-dependent chaperone that facilitates assembly of the eIF2 translation initiation complex by binding to its gamma subunit and enabling proper association with the alpha and beta subunits. Mutations in CDC123 cause autosomal recessive developmental and epileptic encephalopathy with severe developmental delay, infantile spasms, and microcephaly. This gene shows low constraint against loss-of-function variants, consistent with recessive inheritance where heterozygous carriers are typically unaffected.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
3
Pubs (1 yr)
20
P/LP submissions
0%
P/LP missense
0.81
LOEUF
Mechanism
Clinical SummaryCDC123
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
20 unique Pathogenic / Likely Pathogenic· 42 VUS of 99 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.81LOEUF
pLI 0.000
Z-score 2.27
OE 0.50 (0.320.81)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
1.10Z-score
OE missense 0.77 (0.670.89)
143 obs / 185.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.50 (0.320.81)
00.351.4
Missense OE0.77 (0.670.89)
00.61.4
Synonymous OE1.05
01.21.6
LoF obs/exp: 12 / 24.0Missense obs/exp: 143 / 185.0Syn Z: -0.34

ClinVar Variant Classifications

99 submitted variants in ClinVar

Classification Summary

Pathogenic20
VUS42
Likely Benign2
Benign3
20
Pathogenic
42
VUS
2
Likely Benign
3
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
20
0
20
Likely Pathogenic
0
0
0
0
0
VUS
0
35
7
0
42
Likely Benign
0
1
0
1
2
Benign
0
0
3
0
3
Total03630167

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

CDC123 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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