CCN4

Chr 8

cellular communication network factor 4

Also known as: WISP1, WISP1-OT1, WISP1-UT1, WISP1c, WISP1i, WISP1tc

The CCN4 protein is a downstream regulator in the Wnt signaling pathway that promotes cell survival by attenuating p53-mediated apoptosis and upregulating anti-apoptotic proteins. Mutations in CCN4 cause autosomal recessive spondylomegaepiphyseal dysplasia with upper limb mesomelia, joint laxity, and distinctive facies, a skeletal dysplasia syndrome affecting bone and cartilage development. The gene shows low constraint to loss-of-function variation (pLI near 0), consistent with recessive inheritance where heterozygous carriers are typically unaffected.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 1.13
Clinical SummaryCCN4
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.13LOEUF
pLI 0.000
Z-score 1.18
OE 0.69 (0.441.13)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.22Z-score
OE missense 0.96 (0.861.07)
236 obs / 245.5 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.69 (0.441.13)
00.351.4
Missense OE0.96 (0.861.07)
00.61.4
Synonymous OE1.14
01.21.6
LoF obs/exp: 12 / 17.3Missense obs/exp: 236 / 245.5Syn Z: -1.11

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

CCN4 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗