CCDC169-SOHLH2

Chr 13

CCDC169-SOHLH2 readthrough

Also known as: C13orf38-SOHLH2

This gene encodes a fusion protein containing sequences from both C13orf38 and SOHLH2 that arises from natural read-through transcription between these neighboring genes. The gene is highly constrained against loss-of-function variants (pLI = 0.001, LOEUF = 0.61), suggesting it plays an important biological role. No specific disease associations or inheritance patterns have been established for mutations in this fusion gene.

ResearchSummary from RefSeq
LOEUF 0.61
Clinical SummaryCCDC169-SOHLH2
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
49 unique Pathogenic / Likely Pathogenic· 45 VUS of 111 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.61LOEUF
pLI 0.001
Z-score 3.12
OE 0.36 (0.220.61)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
1.03Z-score
OE missense 0.82 (0.730.92)
212 obs / 258.7 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.36 (0.220.61)
00.351.4
Missense OE0.82 (0.730.92)
00.61.4
Synonymous OE0.97
01.21.6
LoF obs/exp: 10 / 27.8Missense obs/exp: 212 / 258.7Syn Z: 0.22

ClinVar Variant Classifications

111 submitted variants in ClinVar

Classification Summary

Pathogenic49
VUS45
Likely Benign13
Benign3
49
Pathogenic
45
VUS
13
Likely Benign
3
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
49
0
49
Likely Pathogenic
0
0
0
0
0
VUS
0
43
2
0
45
Likely Benign
0
7
2
4
13
Benign
0
1
0
2
3
Total051536110

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

CCDC169-SOHLH2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 2 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found