CACNG1

Chr 17

calcium voltage-gated channel auxiliary subunit gamma 1

Also known as: CACNLG

The gamma-1 subunit regulates voltage-gated calcium channels that produce L-type calcium currents in skeletal muscle and controls channel inactivation kinetics during excitation-contraction coupling. Mutations cause congenital myasthenic syndrome with autosomal recessive inheritance. This gene is extremely tolerant to loss-of-function variants, indicating that pathogenic mutations likely affect protein function through other mechanisms.

OMIMResearchSummary from RefSeq, UniProt
GOFmechanismLOEUF 1.82
Clinical SummaryCACNG1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.82LOEUF
pLI 0.000
Z-score -0.54
OE 1.19 (0.741.82)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.32Z-score
OE missense 0.93 (0.811.07)
141 obs / 152.2 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE1.19 (0.741.82)
00.351.4
Missense OE0.93 (0.811.07)
00.61.4
Synonymous OE1.03
01.21.6
LoF obs/exp: 11 / 9.2Missense obs/exp: 141 / 152.2Syn Z: -0.22
DN
0.5674th %ile
GOF
0.6932th %ile
LOF
0.3454th %ile

The highest-scoring mechanism for this gene is gain-of-function.

GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

CACNG1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 2 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found