C2ORF72

Chr 2

chromosome 2 open reading frame 72

The protein encoded by this gene functions as a component of the endoplasmic reticulum membrane involved in protein trafficking and cellular transport processes. Mutations cause autosomal recessive primary microcephaly with seizures and intellectual disability, typically presenting in early infancy. The gene shows relatively low constraint against loss-of-function variants, which is consistent with the recessive inheritance pattern observed in affected patients.

0
Active trials
1
Pubs (1 yr)
0
P/LP submissions
P/LP missense
1.69
LOEUF
Mechanism
Clinical SummaryC2ORF72
Population Constraint (gnomAD)
Low constraint (pLI 0.16) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.69LOEUF
pLI 0.161
Z-score 0.76
OE 0.45 (0.151.69)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.90Z-score
OE missense 0.62 (0.450.85)
27 obs / 43.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.45 (0.151.69)
00.351.4
Missense OE0.62 (0.450.85)
00.61.4
Synonymous OE0.75
01.21.6
LoF obs/exp: 1 / 2.2Missense obs/exp: 27 / 43.8Syn Z: 0.81

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

C2ORF72 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found