C2CD2

Chr 21

C2 calcium dependent domain containing 2

Also known as: C21orf25, C21orf258, TMEM24L

C2CD2 encodes a protein that localizes to the cytosol and nucleus. Mutations cause autosomal recessive intellectual disability and seizures, typically presenting in early childhood. The gene shows moderate constraint against loss-of-function variants, suggesting some tolerance to reduced protein levels.

Summary from RefSeq
Research Assistant →
0
Active trials
0
Pubs (1 yr)
83
P/LP submissions
0%
P/LP missense
0.68
LOEUF
DN
Mechanism· predicted
Clinical SummaryC2CD2
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
78 unique Pathogenic / Likely Pathogenic· 77 VUS of 186 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.68LOEUF
pLI 0.000
Z-score 2.98
OE 0.43 (0.290.68)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
1.21Z-score
OE missense 0.83 (0.760.91)
336 obs / 404.5 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.43 (0.290.68)
00.351.4
Missense OE0.83 (0.760.91)
00.61.4
Synonymous OE1.07
01.21.6
LoF obs/exp: 14 / 32.2Missense obs/exp: 336 / 404.5Syn Z: -0.77
DN
0.6258th %ile
GOF
0.5857th %ile
LOF
0.4038th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

186 submitted variants in ClinVar

Classification Summary

Pathogenic76
Likely Pathogenic2
VUS77
Likely Benign10
Benign5
Conflicting1
76
Pathogenic
2
Likely Pathogenic
77
VUS
10
Likely Benign
5
Benign
1
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
76
0
76
Likely Pathogenic
0
0
2
0
2
VUS
0
72
5
0
77
Likely Benign
0
8
1
1
10
Benign
0
0
1
4
5
Conflicting
1
Total080855171

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

C2CD2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found