C17ORF107

Chr 17

chromosome 17 open reading frame 107

The protein function of C17ORF107 is not well-characterized. Mutations in this gene cause autosomal recessive developmental delay with variable intellectual disability and behavioral abnormalities. The gene shows low constraint against loss-of-function variants, which is consistent with the recessive inheritance pattern observed in affected individuals.

LOEUF 1.50
Clinical SummaryC17ORF107
Population Constraint (gnomAD)
Low constraint (pLI 0.07) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
142 unique Pathogenic / Likely Pathogenic· 159 VUS of 586 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.50LOEUF
pLI 0.069
Z-score 0.93
OE 0.50 (0.201.50)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.50Z-score
OE missense 0.87 (0.731.03)
97 obs / 111.9 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.50 (0.201.50)
00.351.4
Missense OE0.87 (0.731.03)
00.61.4
Synonymous OE0.90
01.21.6
LoF obs/exp: 2 / 4.0Missense obs/exp: 97 / 111.9Syn Z: 0.61

ClinVar Variant Classifications

586 submitted variants in ClinVar

Classification Summary

Pathogenic65
Likely Pathogenic77
VUS159
Likely Benign228
Benign16
Conflicting33
65
Pathogenic
77
Likely Pathogenic
159
VUS
228
Likely Benign
16
Benign
33
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
37
5
23
0
65
Likely Pathogenic
48
25
4
0
77
VUS
1
136
18
4
159
Likely Benign
0
1
131
96
228
Benign
0
1
13
2
16
Conflicting
33
Total86168189102578

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

C17ORF107 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found