C11ORF91

Chr 11

chromosome 11 open reading frame 91

The protein encoded by C11ORF91 functions as a component of the mitochondrial ribosome, specifically involved in mitochondrial protein synthesis. Mutations cause autosomal recessive combined oxidative phosphorylation deficiency-13, characterized by severe early-onset mitochondrial dysfunction with neurological features including developmental delay, seizures, and progressive neurodegeneration. The gene shows low constraint against loss-of-function variants, consistent with its recessive inheritance pattern.

0
Active trials
0
Pubs (1 yr)
20
P/LP submissions
0%
P/LP missense
1.76
LOEUF
Mechanism
Clinical SummaryC11ORF91
Population Constraint (gnomAD)
Low constraint (pLI 0.01) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
20 unique Pathogenic / Likely Pathogenic· 8 VUS of 29 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.76LOEUF
pLI 0.010
Z-score 0.36
OE 0.80 (0.361.76)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.51Z-score
OE missense 0.83 (0.671.03)
58 obs / 70.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.80 (0.361.76)
00.351.4
Missense OE0.83 (0.671.03)
00.61.4
Synonymous OE0.95
01.21.6
LoF obs/exp: 3 / 3.7Missense obs/exp: 58 / 70.0Syn Z: 0.22

ClinVar Variant Classifications

29 submitted variants in ClinVar

Classification Summary

Pathogenic20
VUS8
20
Pathogenic
8
VUS

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
20
0
20
Likely Pathogenic
0
0
0
0
0
VUS
0
3
5
0
8
Likely Benign
0
0
0
0
0
Benign
0
0
0
0
0
Total0325028

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

C11ORF91 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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