C10ORF90

Chr 10

chromosome 10 open reading frame 90

Also known as: FATS, bA422P15.2

The protein functions as a tumor suppressor that maintains the G2/M cell cycle checkpoint after DNA damage by activating p53 through ubiquitin ligase activity and preventing MDM2 binding. Mutations cause autosomal recessive primary microcephaly with seizures and developmental delay, typically presenting in infancy. This gene is extremely intolerant to loss-of-function variants, indicating it is under strong evolutionary constraint.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 1.21
Clinical SummaryC10ORF90
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.21LOEUF
pLI 0.000
Z-score 0.69
OE 0.86 (0.621.21)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.45Z-score
OE missense 1.06 (0.981.15)
432 obs / 406.6 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.86 (0.621.21)
00.351.4
Missense OE1.06 (0.981.15)
00.61.4
Synonymous OE0.95
01.21.6
LoF obs/exp: 24 / 28.0Missense obs/exp: 432 / 406.6Syn Z: 0.55

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

C10ORF90 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC