C10ORF53

Chr 10

chromosome 10 open reading frame 53

The protein encoded by this gene functions in mitochondrial ribosome assembly and is essential for mitochondrial protein synthesis. Mutations cause autosomal recessive mitochondrial complex I deficiency with early-onset encephalomyopathy, developmental delay, and seizures. The gene shows moderate constraint against loss-of-function variants, and affected children typically present in infancy with neurological and muscular manifestations.

0
Active trials
0
Pubs (1 yr)
58
P/LP submissions
P/LP missense
1.07
LOEUF
Mechanism
Clinical SummaryC10ORF53
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.58) — some intolerance to loss-of-function variants.
📋
ClinVar Variants
58 unique Pathogenic / Likely Pathogenic· 32 VUS of 92 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
1.07LOEUF
pLI 0.584
Z-score 1.53
OE 0.00 (0.001.07)
Moderately constrained

Highly tolerant — LoF variants common in population

Missense Constraint
0.46Z-score
OE missense 0.86 (0.701.05)
68 obs / 79.5 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.00 (0.001.07)
00.351.4
Missense OE0.86 (0.701.05)
00.61.4
Synonymous OE0.93
01.21.6
LoF obs/exp: 0 / 2.7Missense obs/exp: 68 / 79.5Syn Z: 0.30

ClinVar Variant Classifications

92 submitted variants in ClinVar

Classification Summary

Pathogenic37
Likely Pathogenic21
VUS32
37
Pathogenic
21
Likely Pathogenic
32
VUS

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories· variant type breakdown unavailable

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
37
Likely Pathogenic
21
VUS
32
Likely Benign
0
Benign
0
Total90

Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

C10ORF53 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 2 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found