BRK1

Chr 3

BRICK1 subunit of SCAR/WAVE actin nucleating complex

Also known as: C3orf10, HSPC300, MDS027, hHBrk1

The protein regulates actin and microtubule organization as part of the WAVE complex that activates the Arp2/3 complex and is required for BDNF-NTRK2 endocytic trafficking and signaling. Mutations cause autosomal recessive developmental and epileptic encephalopathy with brain atrophy, presenting in infancy with seizures, developmental delays, and progressive brain volume loss. The gene shows moderate constraint against loss-of-function variants (LOEUF 0.785).

OMIMResearchSummary from RefSeq, UniProt
MultiplemechanismLOEUF 0.79
Clinical SummaryBRK1
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.69) — some intolerance to loss-of-function variants.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.79LOEUF
pLI 0.687
Z-score 1.81
OE 0.00 (0.000.79)
Moderately constrained

Typical tolerance to LoF variation

Missense Constraint
1.21Z-score
OE missense 0.48 (0.330.69)
20 obs / 42.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.00 (0.000.79)
00.351.4
Missense OE0.48 (0.330.69)
00.61.4
Synonymous OE1.32
01.21.6
LoF obs/exp: 0 / 3.8Missense obs/exp: 20 / 42.0Syn Z: -0.95
DN
0.6161th %ile
GOF
0.6930th %ile
LOF
0.4528th %ile

This gene has evidence for multiple mechanisms of pathogenicity (gain-of-function and dominant-negative). Both the Badonyi & Marsh prediction and the broader genomic evidence point to gain-of-function as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

GOFprediction above median
DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

BRK1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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