BRINP1

Chr 9

BMP/retinoic acid inducible neural specific 1

Also known as: DBC1, DBCCR1, FAM5A

The BRINP1 protein suppresses cell cycle progression in postmitotic neurons by inhibiting G1/S transition and plays a role in neurogenesis and brain development. Loss-of-function mutations cause autosomal dominant neurodevelopmental disorders, as evidenced by the gene's extreme intolerance to loss-of-function variants. The pathogenic mechanism involves haploinsufficiency disrupting normal neuronal cell cycle control and brain development.

Summary from RefSeq, UniProt, Mechanism
0
Active trials
1
Pubs (1 yr)
0
P/LP submissions
P/LP missense
0.28
LOEUF· LoF intol.
LOF
Mechanism· predicted
Clinical SummaryBRINP1
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 0.99). One damaged copy is likely sufficient to cause disease.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.28LOEUF
pLI 0.993
Z-score 4.61
OE 0.12 (0.060.28)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
1.42Z-score
OE missense 0.82 (0.750.89)
383 obs / 469.5 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.12 (0.060.28)
00.351.4
Missense OE0.82 (0.750.89)
00.61.4
Synonymous OE1.07
01.21.6
LoF obs/exp: 4 / 32.3Missense obs/exp: 383 / 469.5Syn Z: -0.79
DN
0.3693th %ile
GOF
0.3788th %ile
LOF
0.67top 25%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.28

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

BRINP1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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