BPIFB2

Chr 20

BPI fold containing family B member 2

Also known as: BPIL1, C20orf184, LPLUNC2, RYSR, dJ726C3.2

This gene encodes a member of the lipid transfer/lipopolysaccharide binding protein family that is highly expressed in hypertrophic tonsils. BPIFB2 is extremely intolerant to loss-of-function variants (pLI near 1.0), but no established human disease associations have been reported for this gene. The clinical significance of BPIFB2 variants in pediatric patients remains unknown.

Summary from RefSeq
Research Assistant →
0
Active trials
1
Pubs (1 yr)
18
P/LP submissions
0%
P/LP missense
1.29
LOEUF
Mechanism
Clinical SummaryBPIFB2
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
18 unique Pathogenic / Likely Pathogenic· 67 VUS of 101 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.29LOEUF
pLI 0.000
Z-score 0.53
OE 0.88 (0.611.29)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.32Z-score
OE missense 0.94 (0.851.05)
257 obs / 272.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.88 (0.611.29)
00.351.4
Missense OE0.94 (0.851.05)
00.61.4
Synonymous OE1.01
01.21.6
LoF obs/exp: 19 / 21.7Missense obs/exp: 257 / 272.1Syn Z: -0.10

ClinVar Variant Classifications

101 submitted variants in ClinVar

Classification Summary

Pathogenic14
Likely Pathogenic4
VUS67
Likely Benign9
Benign1
14
Pathogenic
4
Likely Pathogenic
67
VUS
9
Likely Benign
1
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
14
0
14
Likely Pathogenic
0
0
4
0
4
VUS
0
65
2
0
67
Likely Benign
0
8
0
1
9
Benign
0
0
1
0
1
Total07321195

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

BPIFB2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found