BMT2

Chr 7

S-adenosylmethionine sensor upstream of mTORC1

Also known as: BMT2, C7orf60

The BMT2 protein functions as an S-adenosyl-L-methionine sensor that regulates mTORC1 signaling in response to methionine availability, binding S-adenosyl-L-methionine during methionine sufficiency to promote mTORC1 activity and interacting with GATOR1 and KICSTOR complexes during methionine starvation to inhibit mTORC1. BMT2 is highly constrained against loss-of-function variation (pLI=0.997, LOEUF=0.17), suggesting that mutations in this gene are likely to cause severe disease, though specific associated phenotypes have not yet been established in humans. The inheritance pattern for BMT2-related disorders has not been determined.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
1
Pubs (1 yr)
4
P/LP submissions
P/LP missense
0.17
LOEUF· LoF intol.
Mechanism
Clinical SummaryBMT2
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.
📋
ClinVar Variants
4 unique Pathogenic / Likely Pathogenic· 4 VUS of 8 total submissions
Some data sources returned errors (1)

ensembl: Error: Ensembl fetch failed: 400 for https://rest.ensembl.org/lookup/symbol/homo_sapiens/BMT2?content-type=application/json&expand=1

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.17LOEUF
pLI 0.997
Z-score 3.88
OE 0.00 (0.000.17)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
2.21Z-score
OE missense 0.58 (0.500.67)
124 obs / 215.3 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.00 (0.000.17)
00.351.4
Missense OE0.58 (0.500.67)
00.61.4
Synonymous OE1.00
01.21.6
LoF obs/exp: 0 / 17.5Missense obs/exp: 124 / 215.3Syn Z: 0.02

ClinVar Variant Classifications

8 submitted variants in ClinVar

Classification Summary

Pathogenic3
Likely Pathogenic1
VUS4
3
Pathogenic
1
Likely Pathogenic
4
VUS

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories· variant type breakdown unavailable

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
3
Likely Pathogenic
1
VUS
4
Likely Benign
0
Benign
0
Total8

Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

BMT2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC