B4GALT7

Chr 5AR

beta-1,4-galactosyltransferase 7

Also known as: EDSP1, EDSSLA, EDSSPD1, XGALT1, XGPT, XGPT1

The enzyme attaches the first galactose in the tetrasaccharide linkage region required for proteoglycan biosynthesis, particularly small proteoglycans in skin fibroblasts. Mutations cause spondylodysplastic Ehlers-Danlos syndrome, a connective tissue disorder affecting skeletal development and joint hypermobility with autosomal recessive inheritance. The gene shows low constraint to loss-of-function variation (pLI 0.0001, LOEUF 1.11).

Summary from RefSeq, OMIM, UniProt
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Primary Disease Associations & Inheritance

Ehlers-Danlos syndrome, spondylodysplastic type, 1MIM #130070
AR
0
Active trials
2
Pubs (1 yr)
0
P/LP submissions
P/LP missense
1.11
LOEUF
LOF
Mechanism· G2P
Clinical SummaryB4GALT7
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Gene-Disease Validity (ClinGen)
Ehlers-Danlos syndrome, spondylodysplastic type, 1 · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.11LOEUF
pLI 0.000
Z-score 1.28
OE 0.62 (0.361.11)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.31Z-score
OE missense 1.06 (0.951.18)
227 obs / 214.2 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.62 (0.361.11)
00.351.4
Missense OE1.06 (0.951.18)
00.61.4
Synonymous OE1.08
01.21.6
LoF obs/exp: 8 / 13.0Missense obs/exp: 227 / 214.2Syn Z: -0.58
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveB4GALT7-related spondylo-dysplastic Ehlers Danlos syndromeLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.6356th %ile
GOF
0.5857th %ile
LOF
0.3649th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

B4GALT7 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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