B3GNT7

Chr 2

UDP-GlcNAc:betaGal beta-1,3-N-acetylglucosaminyltransferase 7

Also known as: beta3GnT7

The protein is a N-acetylglucosaminyltransferase that catalyzes the transfer of GlcNAc to galactose residues in keratan sulfate proteoglycans, playing a critical role in corneal keratan sulfate biosynthesis and corneal transparency. Mutations cause autosomal recessive corneal dystrophy with stromal clouding and vision impairment. The gene shows moderate constraint against loss-of-function variants (LOEUF 0.495), indicating intolerance to complete protein loss.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
1
Pubs (1 yr)
28
P/LP submissions
0%
P/LP missense
0.49
LOEUF
Mechanism
Clinical SummaryB3GNT7
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.71) — some intolerance to loss-of-function variants.
📋
ClinVar Variants
28 unique Pathogenic / Likely Pathogenic· 52 VUS of 86 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.49LOEUF
pLI 0.706
Z-score 2.79
OE 0.16 (0.060.49)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
1.19Z-score
OE missense 0.80 (0.710.89)
221 obs / 276.7 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.16 (0.060.49)
00.351.4
Missense OE0.80 (0.710.89)
00.61.4
Synonymous OE1.04
01.21.6
LoF obs/exp: 2 / 12.7Missense obs/exp: 221 / 276.7Syn Z: -0.40

ClinVar Variant Classifications

86 submitted variants in ClinVar

Classification Summary

Pathogenic27
Likely Pathogenic1
VUS52
Likely Benign4
27
Pathogenic
1
Likely Pathogenic
52
VUS
4
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
27
0
27
Likely Pathogenic
0
0
1
0
1
VUS
0
50
2
0
52
Likely Benign
0
3
0
1
4
Benign
0
0
0
0
0
Total05330184

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

B3GNT7 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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