ASMTL

Chr Y

acetylserotonin O-methyltransferase like

Also known as: ASMTLX, ASMTLY, ASTML

The encoded protein functions as a nucleoside triphosphate pyrophosphatase that hydrolyzes various nucleotides including dTTP and UTP, and may also have methyltransferase activity. This gene is located in the pseudoautosomal region of X and Y chromosomes and shows very low constraint against loss-of-function variants. No established human disease associations have been reported for mutations in this gene.

OMIMResearchSummary from RefSeq, UniProt
MultiplemechanismLOEUF 1.00
Clinical SummaryASMTL
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.00LOEUF
pLI 0.000
Z-score 1.57
OE 0.67 (0.461.00)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
-0.61Z-score
OE missense 1.08 (1.001.17)
444 obs / 409.3 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.67 (0.461.00)
00.351.4
Missense OE1.08 (1.001.17)
00.61.4
Synonymous OE1.12
01.21.6
LoF obs/exp: 18 / 26.8Missense obs/exp: 444 / 409.3Syn Z: -1.33
DN
0.7035th %ile
GOF
0.6541th %ile
LOF
0.2484th %ile

This gene has evidence for multiple mechanisms of pathogenicity (dominant-negative and gain-of-function). Both the Badonyi & Marsh prediction and the broader genomic evidence point to dominant-negative as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

DNprediction above median
GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ASMTL · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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