ARL8B

Chr 3

ARF like GTPase 8B

Also known as: ARL10C, Gie1

ARL8B encodes a small GTPase that regulates lysosomal positioning, transport, and fusion, playing critical roles in immune cell cytotoxicity, antigen presentation, and synaptic function. Mutations cause autosomal recessive immunodeficiency with defective cytolytic granule exocytosis and impaired natural killer cell function. The gene shows moderate constraint against loss-of-function variants (LOEUF 0.649), suggesting some tolerance to protein-truncating mutations.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
12
Pubs (1 yr)
78
P/LP submissions
P/LP missense
0.65
LOEUF
Multiple*
Mechanism· predicted
Clinical SummaryARL8B
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.28) despite low pLI — interpret in context.
📋
ClinVar Variants
78 unique Pathogenic / Likely Pathogenic· 23 VUS of 111 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.65LOEUF
pLI 0.130
Z-score 2.49
OE 0.28 (0.140.65)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
2.50Z-score
OE missense 0.31 (0.230.41)
32 obs / 103.6 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.28 (0.140.65)
00.351.4
Missense OE0.31 (0.230.41)
00.61.4
Synonymous OE1.11
01.21.6
LoF obs/exp: 4 / 14.1Missense obs/exp: 32 / 103.6Syn Z: -0.52
DN
0.7131th %ile
GOF
0.6444th %ile
LOF
0.3648th %ile

This gene has evidence for multiple mechanisms of pathogenicity (dominant-negative and gain-of-function). Both the Badonyi & Marsh prediction and the broader genomic evidence point to dominant-negative as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

DNprediction above median
GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

111 submitted variants in ClinVar

Classification Summary

Pathogenic73
Likely Pathogenic5
VUS23
Likely Benign1
73
Pathogenic
5
Likely Pathogenic
23
VUS
1
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories· variant type breakdown unavailable

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
73
Likely Pathogenic
5
VUS
23
Likely Benign
1
Benign
0
Total102

Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ARL8B · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC