ARID2

Chr 12AD

AT-rich interaction domain 2

Also known as: BAF200, CSS6, SMARCF3, ZIPZAP, p200

ARID2 encodes a subunit of the PBAF chromatin remodeling complex that facilitates ligand-dependent transcriptional activation by nuclear receptors and regulates chromatin structure modification. Mutations cause Coffin-Siris syndrome 6, inherited in an autosomal dominant pattern, predominantly through loss-of-function mechanisms. The gene is highly intolerant to loss-of-function variants, consistent with haploinsufficiency as the primary pathogenic mechanism.

OMIMResearchSummary from RefSeq, OMIM, UniProt, Mechanism
LOFmechanismADLOEUF 0.101 OMIM phenotype
Clinical SummaryARID2
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Gene-Disease Validity (ClinGen)
Coffin-Siris syndrome · ADDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.
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Clinical Trials
1 active or recruiting trial — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.10LOEUF
pLI 1.000
Z-score 8.00
OE 0.04 (0.020.10)
Highly constrained

Among the most LoF-intolerant genes (~top 3%)

Missense Constraint
2.73Z-score
OE missense 0.75 (0.710.80)
720 obs / 958.1 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.04 (0.020.10)
00.351.4
Missense OE0.75 (0.710.80)
00.61.4
Synonymous OE1.13
01.21.6
LoF obs/exp: 3 / 80.4Missense obs/exp: 720 / 958.1Syn Z: -1.89
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
strongARID2-related Coffin-Siris like disorderLOFAD
DN
0.2199th %ile
GOF
0.14100th %ile
LOF
0.83top 5%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · 1 literature citation · LOEUF 0.10

Literature Evidence

LOFThe phenotypes of 22 patients with either an ARID2 heterozygous mutation or haploinsufficiency were reviewed.PMID:33051312

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ARID2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗
Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗