ARHGAP19

Chr 10AR

Rho GTPase activating protein 19

Also known as: CMT2KK

This protein functions as a GTPase activator that converts Rho-type GTPases to their inactive GDP-bound state, regulating cellular processes including migration, proliferation, and actin remodeling. Biallelic mutations cause Charcot-Marie-Tooth disease, axonal type 2KK, inherited in an autosomal recessive pattern. The gene shows minimal constraint against loss-of-function variants (pLI near zero), consistent with its recessive inheritance pattern.

OMIMResearchSummary from RefSeq, OMIM, UniProt
ARLOEUF 1.101 OMIM phenotype
Clinical SummaryARHGAP19
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
21 unique Pathogenic / Likely Pathogenic· 72 VUS of 95 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.10LOEUF
pLI 0.000
Z-score 1.15
OE 0.77 (0.551.10)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.34Z-score
OE missense 0.94 (0.851.04)
257 obs / 272.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.77 (0.551.10)
00.351.4
Missense OE0.94 (0.851.04)
00.61.4
Synonymous OE0.82
01.21.6
LoF obs/exp: 22 / 28.6Missense obs/exp: 257 / 272.8Syn Z: 1.39

ClinVar Variant Classifications

95 submitted variants in ClinVar

Classification Summary

Pathogenic20
Likely Pathogenic1
VUS72
Likely Benign2
20
Pathogenic
1
Likely Pathogenic
72
VUS
2
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
1
2
17
0
20
Likely Pathogenic
1
0
0
0
1
VUS
0
67
5
0
72
Likely Benign
0
2
0
0
2
Benign
0
0
0
0
0
Total27122095

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ARHGAP19 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC