ANKMY1

Chr 2

ankyrin repeat and MYND domain containing 1

Also known as: ZMYND13

ANKMY1 encodes a protein predicted to bind zinc ions, though its specific cellular function remains unclear. Mutations cause autosomal recessive developmental delays and intellectual disability, typically with onset in early childhood. The gene shows low constraint against loss-of-function variants, consistent with the recessive inheritance pattern observed in affected individuals.

Summary from RefSeq
Research Assistant →
0
Active trials
1
Pubs (1 yr)
102
P/LP submissions
0%
P/LP missense
1.21
LOEUF
Mechanism
Clinical SummaryANKMY1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
100 unique Pathogenic / Likely Pathogenic· 207 VUS of 366 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.21LOEUF
pLI 0.000
Z-score 0.44
OE 0.93 (0.711.21)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.26Z-score
OE missense 1.03 (0.961.10)
587 obs / 569.7 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.93 (0.711.21)
00.351.4
Missense OE1.03 (0.961.10)
00.61.4
Synonymous OE1.00
01.21.6
LoF obs/exp: 38 / 41.0Missense obs/exp: 587 / 569.7Syn Z: 0.04

ClinVar Variant Classifications

366 submitted variants in ClinVar

Classification Summary

Pathogenic92
Likely Pathogenic8
VUS207
Likely Benign20
Benign4
92
Pathogenic
8
Likely Pathogenic
207
VUS
20
Likely Benign
4
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
92
0
92
Likely Pathogenic
0
0
8
0
8
VUS
1
195
11
0
207
Likely Benign
0
19
0
1
20
Benign
0
1
0
3
4
Total12151114331

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ANKMY1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found