ALG5

Chr 13AD

ALG5 dolichyl-phosphate beta-glucosyltransferase

Also known as: PKD7, bA421P11.2

The ALG5 protein is a dolichyl-phosphate beta-glucosyltransferase that produces the glucose donor substrate essential for the final steps of N-linked protein glycosylation in the endoplasmic reticulum. Mutations cause polycystic kidney disease 7, which follows autosomal dominant inheritance. The gene shows significant constraint against loss-of-function variants (LOEUF 0.453), indicating that complete loss of ALG5 function is likely incompatible with normal development.

GeneReviewsOMIMResearchSummary from RefSeq, OMIM, UniProt
ADLOEUF 0.451 OMIM phenotype
Clinical SummaryALG5
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Gene-Disease Validity (ClinGen)
autosomal dominant polycystic kidney disease · ADModerate

Moderate evidence — consider for supplementary testing

Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.22) despite low pLI — interpret in context.
📋
ClinVar Variants
58 unique Pathogenic / Likely Pathogenic· 48 VUS of 131 total submissions
📖
GeneReview available — ALG5
Authoritative clinical overview · Recommended first read
Open GeneReview ↗

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.45LOEUF
pLI 0.463
Z-score 3.50
OE 0.22 (0.110.45)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
1.01Z-score
OE missense 0.79 (0.690.91)
143 obs / 181.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.22 (0.110.45)
00.351.4
Missense OE0.79 (0.690.91)
00.61.4
Synonymous OE1.04
01.21.6
LoF obs/exp: 5 / 23.2Missense obs/exp: 143 / 181.1Syn Z: -0.28

ClinVar Variant Classifications

131 submitted variants in ClinVar

Classification Summary

Pathogenic55
Likely Pathogenic3
VUS48
Likely Benign8
Benign3
55
Pathogenic
3
Likely Pathogenic
48
VUS
8
Likely Benign
3
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
2
3
50
0
55
Likely Pathogenic
3
0
0
0
3
VUS
1
43
4
0
48
Likely Benign
0
6
0
2
8
Benign
0
0
1
2
3
Total652554117

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ALG5 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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