ALG11

Chr 13AR

ALG11 alpha-1,2-mannosyltransferase

Also known as: CDG1P, GT8

The protein functions as a GDP-mannose:Man3GlcNAc2-PP-dolichol-alpha1,2-mannosyltransferase that catalyzes the transfer of the fourth and fifth mannose residues to dolichol-linked oligosaccharides on the cytosolic side of the endoplasmic reticulum during N-linked glycosylation. Mutations cause congenital disorder of glycosylation type Ip (CDG-Ip) through autosomal recessive inheritance. The pathogenic mechanism involves disruption of the early steps of N-linked protein glycosylation due to defective mannosyltransferase activity.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 1.331 OMIM phenotype
Clinical SummaryALG11
🧬
Gene-Disease Validity (ClinGen)
ALG11-congenital disorder of glycosylation · ARModerate

Moderate evidence — consider for supplementary testing

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.33LOEUF
pLI 0.000
Z-score 0.56
OE 0.85 (0.561.33)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.05Z-score
OE missense 1.01 (0.911.12)
258 obs / 255.9 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.85 (0.561.33)
00.351.4
Missense OE1.01 (0.911.12)
00.61.4
Synonymous OE0.90
01.21.6
LoF obs/exp: 14 / 16.5Missense obs/exp: 258 / 255.9Syn Z: 0.79

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ALG11 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →