ALG1

Chr 16AR

ALG1 chitobiosyldiphosphodolichol beta-mannosyltransferase

Also known as: CDG1K, HMAT1, HMT-1, HMT1, MT-1, Mat-1, hMat-1

The encoded enzyme catalyzes the first mannosylation step in the biosynthesis of lipid-linked oligosaccharides in the endoplasmic reticulum membrane. Biallelic mutations cause congenital disorder of glycosylation type Ik, inherited in an autosomal recessive pattern. The pathogenesis involves disrupted N-linked protein glycosylation due to defective oligosaccharide precursor synthesis.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 1.501 OMIM phenotype
Clinical SummaryALG1
🧬
Gene-Disease Validity (ClinGen)
ALG1-congenital disorder of glycosylation · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.50LOEUF
pLI 0.000
Z-score -0.41
OE 1.09 (0.801.50)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-2.05Z-score
OE missense 1.35 (1.241.48)
357 obs / 263.5 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.09 (0.801.50)
00.351.4
Missense OE1.35 (1.241.48)
00.61.4
Synonymous OE1.45
01.21.6
LoF obs/exp: 27 / 24.8Missense obs/exp: 357 / 263.5Syn Z: -3.74

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ALG1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →