ALDOB

Chr 9AR

aldolase, fructose-bisphosphate B

Also known as: ALDB, ALDO2

The protein is a tetrameric glycolytic enzyme that catalyzes the reversible conversion of fructose-1,6-bisphosphate to glyceraldehyde 3-phosphate and dihydroxyacetone phosphate, with the B isoform specifically expressed in adult liver, kidney and intestine. Mutations cause hereditary fructose intolerance through an autosomal recessive inheritance pattern. The pathogenic mechanism involves dominant negative effects where mutant protein subunits disrupt the function of the tetrameric enzyme complex.

OMIMResearchSummary from RefSeq, OMIM, UniProt, Mechanism
DNmechanismARLOEUF 1.101 OMIM phenotype
Clinical SummaryALDOB
🧬
Gene-Disease Validity (ClinGen)
hereditary fructose intolerance · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.10LOEUF
pLI 0.000
Z-score 1.25
OE 0.68 (0.431.10)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-1.42Z-score
OE missense 1.28 (1.161.42)
255 obs / 198.6 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.68 (0.431.10)
00.351.4
Missense OE1.28 (1.161.42)
00.61.4
Synonymous OE1.25
01.21.6
LoF obs/exp: 12 / 17.7Missense obs/exp: 255 / 198.6Syn Z: -1.68
DN
0.76top 25%
GOF
0.4579th %ile
LOF
0.2970th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ALDOB · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →