AK4

Chr 1

adenylate kinase 4

Also known as: AK 4, AK3, AK3L1, AK3L2

The protein functions as a broad-specificity mitochondrial nucleoside phosphate kinase that maintains cellular nucleotide homeostasis by catalyzing phosphate transfers between nucleotides, particularly converting AMP to ADP using ATP as a phosphate donor, and plays a protective role against oxidative stress. Mutations cause reticular dysgenesis, a severe combined immunodeficiency with sensorineural hearing loss that presents in infancy. This condition follows autosomal recessive inheritance.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
17
Pubs (1 yr)
0
P/LP submissions
P/LP missense
LOEUF
DN
Mechanism· predicted
Some data sources returned errors (1)

gnomad: TimeoutError: The operation was aborted due to timeout

Population Genetics & Constraint

Constraint data not available from gnomAD.

DN
0.77top 25%
GOF
0.6150th %ile
LOF
0.2775th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

AK4 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →