AFAP1

Chr 4

actin filament associated protein 1

Also known as: AFAP, AFAP-110, AFAP110

The AFAP1 protein cross-links actin filaments and functions as an adapter molecule linking signaling proteins like SRC and PKC to the actin cytoskeleton. Mutations cause autosomal dominant developmental delays, intellectual disability, and distinctive facial features. The gene shows moderate constraint against loss-of-function variants.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
23
Pubs (1 yr)
0
P/LP submissions
P/LP missense
0.67
LOEUF
DN
Mechanism· predicted
Clinical SummaryAFAP1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.67LOEUF
pLI 0.000
Z-score 3.24
OE 0.45 (0.310.67)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
-0.91Z-score
OE missense 1.11 (1.041.20)
558 obs / 500.8 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.45 (0.310.67)
00.351.4
Missense OE1.11 (1.041.20)
00.61.4
Synonymous OE1.26
01.21.6
LoF obs/exp: 18 / 40.1Missense obs/exp: 558 / 500.8Syn Z: -3.01
DN
0.6937th %ile
GOF
0.6247th %ile
LOF
0.4528th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

AFAP1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →