ADSL

Chr 22AR

adenylosuccinate lyase

Also known as: AMPS, ASASE, ASL

The encoded protein catalyzes two non-sequential reactions in the de novo purine biosynthetic pathway, converting SAICAR to AICAR and adenylosuccinate to adenosine monophosphate. Autosomal recessive mutations cause adenylosuccinase deficiency, characterized by psychomotor retardation, epilepsy, and autistic features. The pathogenic mechanism involves loss of enzyme function disrupting purine metabolism.

OMIMResearchSummary from RefSeq, OMIM, UniProt, Mechanism
DNmechanismARLOEUF 1.071 OMIM phenotype
Clinical SummaryADSL
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Gene-Disease Validity (ClinGen)
adenylosuccinate lyase deficiency · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
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Clinical Trials
1 active or recruiting trial — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.07LOEUF
pLI 0.000
Z-score 1.26
OE 0.74 (0.531.07)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.80Z-score
OE missense 0.87 (0.780.96)
244 obs / 281.9 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.74 (0.531.07)
00.351.4
Missense OE0.87 (0.780.96)
00.61.4
Synonymous OE0.87
01.21.6
LoF obs/exp: 21 / 28.2Missense obs/exp: 244 / 281.9Syn Z: 1.05
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveADSL-related adenylosuccinase deficiencyOTHERAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.6937th %ile
GOF
0.5562th %ile
LOF
0.4038th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ADSL · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
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