ADGRB1

Chr 8

adhesion G protein-coupled receptor B1

Also known as: BAI1, GDAIF

ADGRB1 encodes a phosphatidylserine receptor that functions in apoptotic cell clearance, synaptic plasticity regulation, dendritic spine formation, and angiogenesis inhibition in the brain. Mutations cause autosomal recessive developmental and epileptic encephalopathy with movement abnormalities. This gene is highly constrained against loss-of-function variants (pLI 1.0, LOEUF 0.14), indicating that haploinsufficiency is likely not tolerated.

OMIMResearchSummary from RefSeq, UniProt
LOFmechanismLOEUF 0.14
Clinical SummaryADGRB1
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Dual constrained — LoF & missense intolerant
LoF Constraint
0.14LOEUF
pLI 1.000
Z-score 7.03
OE 0.06 (0.030.14)
Highly constrained

Among the most LoF-intolerant genes (~top 3%)

Missense Constraint
4.48Z-score
OE missense 0.58 (0.540.62)
515 obs / 891.5 exp
Constrained

Highly missense-constrained (top ~0.1%)

Observed / Expected Ratios
LoF OE0.06 (0.030.14)
00.351.4
Missense OE0.58 (0.540.62)
00.61.4
Synonymous OE1.05
01.21.6
LoF obs/exp: 4 / 65.4Missense obs/exp: 515 / 891.5Syn Z: -0.78
DN
0.3892th %ile
GOF
0.5955th %ile
LOF
0.69top 10%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.14

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ADGRB1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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