ADAMTS3

Chr 4AR

ADAM metallopeptidase with thrombospondin type 1 motif 3

Also known as: ADAMTS-4, HKLLS3

This protein cleaves propeptides of type II collagen prior to fibril assembly and does not act on types I and III collagens. Mutations cause Hennekam lymphangiectasia-lymphedema syndrome 3, which involves lymphatic abnormalities and connective tissue defects. The gene follows autosomal recessive inheritance and shows minimal constraint against loss-of-function variants (very low pLI score).

OMIMResearchSummary from RefSeq, OMIM, UniProt
DNmechanismARLOEUF 0.601 OMIM phenotype
Clinical SummaryADAMTS3
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
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Clinical Trials
2 active or recruiting trials — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.60LOEUF
pLI 0.000
Z-score 4.13
OE 0.44 (0.330.60)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.55Z-score
OE missense 0.94 (0.881.00)
641 obs / 681.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.44 (0.330.60)
00.351.4
Missense OE0.94 (0.881.00)
00.61.4
Synonymous OE0.97
01.21.6
LoF obs/exp: 28 / 63.5Missense obs/exp: 641 / 681.0Syn Z: 0.38
DN
0.6454th %ile
GOF
0.5661th %ile
LOF
0.3355th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ADAMTS3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗