ACSM4

Chr 12

acyl-CoA synthetase medium chain family member 4

ACSM4 encodes a mitochondrial enzyme that activates medium-chain fatty acids (C6-12) by conjugating them with coenzyme A, representing the first step in fatty acid metabolism. The gene shows very low constraint against loss-of-function variants, and no definitive disease associations have been established in humans. Clinical significance of ACSM4 variants remains unclear at this time.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
0
Pubs (1 yr)
46
P/LP submissions
0%
P/LP missense
1.24
LOEUF
DN
Mechanism· predicted
Clinical SummaryACSM4
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
45 unique Pathogenic / Likely Pathogenic· 75 VUS of 130 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.24LOEUF
pLI 0.000
Z-score 0.47
OE 0.91 (0.681.24)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.91Z-score
OE missense 0.86 (0.780.95)
274 obs / 319.7 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.91 (0.681.24)
00.351.4
Missense OE0.86 (0.780.95)
00.61.4
Synonymous OE0.85
01.21.6
LoF obs/exp: 30 / 32.9Missense obs/exp: 274 / 319.7Syn Z: 1.24
DN
0.7132th %ile
GOF
0.5563th %ile
LOF
0.4038th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

130 submitted variants in ClinVar

Classification Summary

Pathogenic43
Likely Pathogenic2
VUS75
Likely Benign4
43
Pathogenic
2
Likely Pathogenic
75
VUS
4
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
43
0
43
Likely Pathogenic
0
0
2
0
2
VUS
0
66
9
0
75
Likely Benign
0
3
0
1
4
Benign
0
0
0
0
0
Total069541124

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ACSM4 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC
ACSM4 polymorphisms are associated with rapid AIDS progression in HIV-infected patients.
Guzmán-Fulgencio M et al.·J Acquir Immune Defic Syndr
2014Cohort