ACKR3

Chr 2AR

atypical chemokine receptor 3

Also known as: CMKOR1, CXC-R7, CXCR-7, CXCR7, GPR159, RDC-1, RDC1

ACKR3 encodes an atypical chemokine receptor that regulates chemokine levels through high-affinity binding and internalization, and controls axon guidance in the oculomotor system by regulating CXCL12 levels. Mutations cause oculomotor-abducens synkinesis with autosomal recessive inheritance. This gene has moderate constraint against loss-of-function variants (LOEUF 0.68).

Summary from RefSeq, OMIM, UniProt
Research Assistant →

Primary Disease Associations & Inheritance

?Oculomotor-abducens synkinesisMIM #619215
AR
0
Active trials
42
Pubs (1 yr)
71
P/LP submissions
1%
P/LP missense
LOEUF
Multiple*
Mechanism· predicted
Clinical SummaryACKR3
📋
ClinVar Variants
70 unique Pathogenic / Likely Pathogenic· 43 VUS of 128 total submissions
Some data sources returned errors (1)

gnomad: TimeoutError: The operation was aborted due to timeout

Population Genetics & Constraint

Constraint data not available from gnomAD.

DN
0.7230th %ile
GOF
0.79top 25%
LOF
0.2871th %ile

This gene has evidence for multiple mechanisms of pathogenicity (gain-of-function and dominant-negative). Both the Badonyi & Marsh prediction and the broader genomic evidence point to gain-of-function as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

GOFprediction above median
DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

128 submitted variants in ClinVar

Classification Summary

Pathogenic69
Likely Pathogenic1
VUS43
Likely Benign9
Benign3
Conflicting1
69
Pathogenic
1
Likely Pathogenic
43
VUS
9
Likely Benign
3
Benign
1
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
1
68
0
69
Likely Pathogenic
0
0
1
0
1
VUS
0
35
8
0
43
Likely Benign
0
4
5
0
9
Benign
0
1
0
2
3
Conflicting
1
Total041822126

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ACKR3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗
Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗