ABHD3

Chr 18

abhydrolase domain containing 3, phospholipase

Also known as: LABH3

The protein encoded by this gene is a phospholipase that cleaves myristate-containing phosphatidylcholines and other medium-chain phospholipids, contributing to phospholipid remodeling. Biallelic mutations cause autosomal recessive spastic paraplegia with intellectual disability and seizures, typically presenting in early childhood. The gene shows very low constraint against loss-of-function variants (pLI near 0), consistent with recessive inheritance requiring biallelic mutations for disease manifestation.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
2
Pubs (1 yr)
33
P/LP submissions
0%
P/LP missense
1.18
LOEUF
Mechanism
Clinical SummaryABHD3
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
31 unique Pathogenic / Likely Pathogenic· 52 VUS of 97 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.18LOEUF
pLI 0.000
Z-score 0.94
OE 0.78 (0.531.18)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.57Z-score
OE missense 0.89 (0.791.00)
186 obs / 209.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.78 (0.531.18)
00.351.4
Missense OE0.89 (0.791.00)
00.61.4
Synonymous OE0.89
01.21.6
LoF obs/exp: 16 / 20.6Missense obs/exp: 186 / 209.1Syn Z: 0.76

ClinVar Variant Classifications

97 submitted variants in ClinVar

Classification Summary

Pathogenic30
Likely Pathogenic1
VUS52
Benign1
30
Pathogenic
1
Likely Pathogenic
52
VUS
1
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
30
0
30
Likely Pathogenic
0
0
1
0
1
VUS
0
45
7
0
52
Likely Benign
0
0
0
0
0
Benign
0
0
0
1
1
Total04538184

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ABHD3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC