ABHD18

Chr 4

abhydrolase domain containing 18

Also known as: C4orf29

ABHD18 encodes a mitochondrial hydrolase enzyme involved in lipid metabolism. Mutations cause autosomal recessive developmental and epileptic encephalopathy with movement abnormalities, typically presenting in infancy with seizures, developmental delay, and neurodegeneration. The gene shows moderate constraint against loss-of-function variants.

Summary from RefSeq
Research Assistant →
0
Active trials
2
Pubs (1 yr)
29
P/LP submissions
0%
P/LP missense
1.28
LOEUF
Mechanism
Clinical SummaryABHD18
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
29 unique Pathogenic / Likely Pathogenic· 64 VUS of 124 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.28LOEUF
pLI 0.000
Z-score 0.53
OE 0.88 (0.621.28)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.99Z-score
OE missense 0.81 (0.710.92)
163 obs / 202.5 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.88 (0.621.28)
00.351.4
Missense OE0.81 (0.710.92)
00.61.4
Synonymous OE0.81
01.21.6
LoF obs/exp: 20 / 22.7Missense obs/exp: 163 / 202.5Syn Z: 1.21

ClinVar Variant Classifications

124 submitted variants in ClinVar

Classification Summary

Pathogenic27
Likely Pathogenic2
VUS64
Likely Benign4
Benign3
27
Pathogenic
2
Likely Pathogenic
64
VUS
4
Likely Benign
3
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
27
0
27
Likely Pathogenic
0
0
2
0
2
VUS
0
53
11
0
64
Likely Benign
0
0
2
2
4
Benign
0
0
3
0
3
Total053452100

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ABHD18 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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