ABCD1

Chr XXLR

ATP binding cassette subfamily D member 1

Also known as: ABC42, ALD, ALDP, AMN

The ABCD1 protein is a peroxisomal membrane transporter that imports very long chain fatty acids into peroxisomes for catabolism. Mutations cause X-linked recessive adrenoleukodystrophy and adrenomyeloneuropathy through accumulation of very long chain fatty acids that damage myelin and adrenal cortex. Loss-of-function mutations disrupt peroxisomal fatty acid transport, leading to toxic buildup of these lipids in tissues.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismXLRLOEUF 0.152 OMIM phenotypes
VCEP Guidelines: Peroxisomal DisordersReleased
ClinGen Panel
Clinical SummaryABCD1
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Gene-Disease Validity (ClinGen)
adrenoleukodystrophy · XLDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.
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Clinical Trials
6 active or recruiting trials — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.15LOEUF
pLI 0.999
Z-score 4.13
OE 0.00 (0.000.15)
Highly constrained

Among the most LoF-intolerant genes (~top 3%)

Missense Constraint
1.87Z-score
OE missense 0.72 (0.650.80)
250 obs / 347.9 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.00 (0.000.15)
00.351.4
Missense OE0.72 (0.650.80)
00.61.4
Synonymous OE0.96
01.21.6
LoF obs/exp: 0 / 19.9Missense obs/exp: 250 / 347.9Syn Z: 0.44

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ABCD1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗